Introduction
A foreign body in the gastrointestinal tract may lead to abdominal pain, halitosis, obstruction, or perforation [1]. Bezoars are foreign bodies that are said to accumulate slowly in the gastrointestinal tract, especially in the stomach [2, 3]. The overall prevalence of bezoars is less than 0.5% of upper digestive tract endoscopy [4]. Trichobezoars make up 55% of all bezoars [5] and 90% of all trichobezoars occur in female cases [6]. Bezoar formation in a healthy person is rare and typically is seen in young women who have psychiatric disorders [7]. Case report
A 9-year-old girl was referred to the surgery ward in Ahvaz Apadana hospital for evaluation following a history of vomiting, persistent weight loss and stomach fullness over the past 5 months. She had no history of psychiatric disorders. Endoscopy of the upper digestive tract revealed a blackened mobile mass blocking passage of the endoscope. In addition, the computed tomography (CT) showed a hypodense circular 25 cm × 15 cm mass including gas bubbles in the stomach (Figure 1).
Surgical treatment was initiated by general anaesthesia, which was done due to the finding of a large intragastric mass in the form of the stomach. Gastrotomy was performed and a trichobezoar composed of strands of hair was removed (Figure 2). The patient progressed with no complications and was discharged from hospital 3 days after surgery. Discussion
The literature previously confirmed that most bezoars occur in young women with psychiatric disorders [7]. Ali et al. reported two cases of Rapunzel syndrome, with and without psychiatric disorder [8]. The patient in this report had no psychiatric disorder. The diagnosis is usually made by upper digestive tract endoscopy and confirmed by computed tomography, but in cases in which the endoscopic passage is blocked, such as the present case, physical examination associated with computed tomography is helpful. One option for treatment and management of trichobezoars is to try to dissolve the materials, but the type of surgery is dependent on the size of the mass. A small trichobezoar may removed by endoscopy. However, in the case of large masses, this method is less likely to be successful. Thus, in such cases the stomach cavity had to be opened and gastrostomy performed, as has been described in the literature [9, 10].
In conclusion, because of the rarity of gastrointestinal tumours in children and adolescents, in the case of dealing with an abdominal mass in young patients, usually Rapunzel syndrome should be taken into consideration in the investigation of cases with history of vomiting, persistent weight loss and anaemia. Also, we must keep in mind the possibility of foreign bodies if there is unusual presentation of gastrointestinal problems. Diagnosis and treatment should include endoscopy with computed tomography and surgical management in most cases. References
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